Faculty, Staff and Student Publications

Language

English

Publication Date

2-23-2024

Journal

Head and Neck Pathology

DOI

10.1007/s12105-024-01612-x

PMID

38393488

PMCID

PMC10891012

PubMedCentral® Posted Date

2-23-2024

PubMedCentral® Full Text Version

Post-print

Abstract

Background: Pleomorphic adenoma is a well-known benign salivary gland neoplasm characterized by the presence of varying proportions of three different components, including bi-layered ducts, myoepithelial cells, and admixed within a chondromyxoid/fibrous stroma.

Method: We report an interesting case of an adult male who presented with bleeding from an extensively degenerated parotid gland mass, concerning for a vascular neoplasm versus primary malignant tumor. Microscopically, majority of the viable tumor exhibited diffuse proliferation of spindle to epithelioid cells, with focal areas depicting cribriform glands, ducts, and scant chondromyxoid stroma.

Result: Next-generation sequencing (NGS) RNA-based fusion panel analysis identified a gene rearrangement involving the pleomorphic adenoma gene 1 (PLAG1), with a novel, cryptogenic fusion partner known as LINC01606; [LINC01606::PLAG1; inv(8;8)(8q12.1;8q12.1)].

Conclusion: To the best of our knowledge, this is the first documented case of a long non-coding RNA (lnc-RNA) serving as a rearrangement partner with the PLAG1 gene. We reviewed the molecular characteristics of this entity and explored the potential role of LINC01606::PLAG1 in the tumorigenesis of pleomorphic adenoma.

Keywords

Adult, Male, Humans, Adenoma, Pleomorphic, DNA-Binding Proteins, Salivary Gland Neoplasms, Gene Rearrangement, RNA, Pleomorphic adenoma, PLAG1, Gene rearrangement, LINC01606

Published Open-Access

yes

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