Language

English

Publication Date

1-16-2026

Journal

iScience

DOI

10.1016/j.isci.2025.114388

PMID

41561374

PMCID

PMC12814433

PubMedCentral® Posted Date

12-11-2025

PubMedCentral® Full Text Version

Post-print

Abstract

The dopaminergic system has a large role in behavior and neurological disease, and understanding dopamine level regulation in vivo is critical. To identify dopamine regulators, we utilized Drosophila melanogaster cuticle pigmentation, where dopamine is a precursor to melanin. We measured dopamine from known pigmentation mutants (e.g., tanebonyblack) and performed an RNAi-based screen to identify additional regulators. We found 153 hits, enriched for developmental signaling pathways and mitochondria-associated proteins. From 35 prioritized candidates, 11 affected head dopamine levels. Effects on brain dopamine were mild, even knocking down the rate-limiting synthesis enzyme Tyrosine hydroxylase (TH), suggesting dopamine levels are tightly regulated in the nervous system. We pursued two hits that reduced brain dopamine levels, clueless and mask. Further examination suggests that the mask regulates the transcription of TH and affects dopamine-dependent sleep. In summary, studying genes that affect cuticle pigmentation helped to identify genes that alter dopamine metabolism and a behavioral regulator.

Keywords

model organism, neuroscience

Published Open-Access

yes

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