Faculty, Staff and Student Publications

Authors

Denise G O'Mahony
Susan J Ramus
Melissa C Southey
Nicola S Meagher
Andreas Hadjisavvas
Esther M John
Ute Hamann
Evgeny N Imyanitov
Irene L Andrulis
Priyanka Sharma
Mary B Daly
Christopher R Hake
Jeffrey N Weitzel
Anna Jakubowska
Andrew K Godwin
Adalgeir Arason
Anita Bane
Jacques Simard
Penny Soucy
Maria A Caligo
Phuong L Mai
Kathleen B M Claes
Manuel R Teixeira
Wendy K Chung
Conxi Lazaro
Peter J Hulick
Amanda E Toland
Inge Sokilde Pedersen
Susan L Neuhausen
Ana Vega
Miguel de la Hoya
Heli Nevanlinna
Mallika Dhawan
Valentina Zampiga
Rita Danesi
Liliana Varesco
Viviana Gismondi
Valerio Gaetano Vellone
Paul A James
Ramunas Janavicius
Liene Nikitina-Zake
Finn Cilius Nielsen
Thomas van Overeem Hansen
Tanja Pejovic
Ake Borg
Johanna Rantala
Kenneth Offit
Marco Montagna
Katherine L Nathanson
Susan M Domchek
Ana Osorio
María J García
Beth Y Karlan
GEMO Study Collaborators
Anna De Fazio
David Bowtell
AOCS Group
Lesley McGuffog
Michael T Parsons
Thilo Dörk
Lisa-Marie Speith
Elizabeth Santana Dos Santos
Alexandre André B A da Costa
Paolo Radice
Paolo Peterlongo
Laura Papi
Christoph Engel
Eric Hahnen
Rita K Schmutzler
Barbara Wappenschmidt
Douglas F Easton
Marc Tischkowitz
Christian F Singer
Yen Yen Tan
Alice S Whittemore
Weiva Sieh
James D Brenton
Drakoulis Yannoukakos
Florentia Fostira
Irene Konstantopoulou
Jana Soukupova
Michal Vocka
CZECANCA Consortium
Georgia Chenevix-Trench
Paul D P Pharoah
Antonis C Antoniou
David E Goldgar
Amanda B Spurdle
Kyriaki Michailidou
Consortium of Investigators of Modifiers of BRCA1/2
Evidence-based Network for the Interpretation of Germline Mutant Alleles Consortium
HEBOn Investigators
Goska Leslie

Publication Date

6-1-2023

Journal

British Journal of Cancer

Abstract

BACKGROUND: The distribution of ovarian tumour characteristics differs between germline BRCA1 and BRCA2 pathogenic variant carriers and non-carriers. In this study, we assessed the utility of ovarian tumour characteristics as predictors of BRCA1 and BRCA2 variant pathogenicity, for application using the American College of Medical Genetics and the Association for Molecular Pathology (ACMG/AMP) variant classification system.

METHODS: Data for 10,373 ovarian cancer cases, including carriers and non-carriers of BRCA1 or BRCA2 pathogenic variants, were collected from unpublished international cohorts and consortia and published studies. Likelihood ratios (LR) were calculated for the association of ovarian cancer histology and other characteristics, with BRCA1 and BRCA2 variant pathogenicity. Estimates were aligned to ACMG/AMP code strengths (supporting, moderate, strong).

RESULTS: No histological subtype provided informative ACMG/AMP evidence in favour of BRCA1 and BRCA2 variant pathogenicity. Evidence against variant pathogenicity was estimated for the mucinous and clear cell histologies (supporting) and borderline cases (moderate). Refined associations are provided according to tumour grade, invasion and age at diagnosis.

CONCLUSIONS: We provide detailed estimates for predicting BRCA1 and BRCA2 variant pathogenicity based on ovarian tumour characteristics. This evidence can be combined with other variant information under the ACMG/AMP classification system, to improve classification and carrier clinical management.

Keywords

Humans, Female, Virulence, BRCA1 Protein, BRCA2 Protein, Ovarian Neoplasms, Genetic Predisposition to Disease, Breast Neoplasms

Comments

Associated Data

PMID: 37076566

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