Faculty, Staff and Student Publications

Language

English

Publication Date

10-2-2025

Journal

Scientific Reports

DOI

10.1038/s41598-025-16889-3

PMID

41038921

PMCID

PMC12491558

PubMedCentral® Posted Date

10-2-2025

PubMedCentral® Full Text Version

Post-print

Abstract

Leptomeningeal disease (LMD) is a subtype of central nervous system metastatic disease that is associated with poor patient outcomes and limited treatment options. There is an unmet need to develop preclinical models of LMD to expedite and improve the development of new therapeutics. Here, we describe the development of multiple orthotopic immunocompetent murine models of melanoma LMD, including their use to assess the efficacy of systemic and/or intrathecal immunotherapy. LMD was established by direct intrathecal injection of murine cell lines (B16-F10, BP, D4M, D4M-UV2, MC38-gp100, RMS, YUMM3.1, and YUMMER1.7) into the cisterna magna of C57BL/6 mice. Tumor take rate, distribution, histology, peri-procedural mortality, and animal survival were assessed for each cell line. Intrathecal and systemic treatment with anti-PD1 were tested for safety, efficacy, and immune infiltration for LMD. Cisternal injection of murine melanoma cell lines successfully established LMD with low peri-procedural mortality, high tumor take rate, and varied survival duration across the panel of cell lines. Decreasing the total number of cells injected and increasing the volume of suspension of the injected cells increased the rate of distal spinal cord deposits, reflecting the common clinical distribution of LMD. Intrathecal administration of anti-PD1 in non-tumor bearing mice caused no morbidity or toxicity. Concurrent intrathecal and systemic anti-PD1 immunotherapy increased the survival of mice with murine melanoma LMD. We have established and characterized several immunocompetent murine models of LMD to facilitate the development and testing of new, more effective immunotherapy strategies for melanoma patients with LMD.

Keywords

Animals, Mice, Immune Checkpoint Inhibitors, Cell Line, Tumor, Disease Models, Animal, Meningeal Neoplasms, Injections, Spinal, Mice, Inbred C57BL, Melanoma, Melanoma, Experimental, Immunotherapy, Female, Programmed Cell Death 1 Receptor, Leptomeningeal disease, Melanoma, Intrathecal, anti-PD1, Immunotherapy, Cancer, Cancer models, CNS cancer, Metastasis

Published Open-Access

yes

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